The importance of functional tests to assess the effect of a new CFTR variant when genotype–phenotype correlation is not possible

نویسندگان

  • Alexandre Hinzpeter
  • Marie‐Pierre Reboul
  • Isabelle Callebaut
  • Cécile Zordan
  • Bruno Costes
  • Julie Guichoux
  • Albert Iron
  • Didier Lacombe
  • Natacha Martin
  • Benoit Arveiler
  • Pascale Fanen
  • Patricia Fergelot
  • Emmanuelle Girodon
چکیده

In vitro functional tests aimed to investigate CFTR dysfunction appear critical to help elucidate the functional impact of new variants of uncertain clinical significance and solve inconclusive cases, especially in early deceased newborns.

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عنوان ژورنال:

دوره 5  شماره 

صفحات  -

تاریخ انتشار 2017